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Menkes' disease with a Dandy-Walker variant: case report

M Bekiesiñska-Figatowska1, D Rokicki, J Walecki

  • 1Department of Diagnostic Imaging, Central Railway Hospital, Warsaw, Poland. m.figatowska@mp.pl

Neuroradiology
|January 5, 2002
PubMed

Insights

This study details a boy with Menkes disease, highlighting MRI findings of delayed myelination, brain atrophy, and tortuous vessels. These characteristic signs were observed alongside a Dandy-Walker variant.

Area of Science:

  • Neurology
  • Pediatric Radiology
  • Medical Genetics

Background:

  • Menkes disease is a rare X-linked genetic disorder affecting copper metabolism.
  • It typically presents in infancy with neurological deficits and connective tissue abnormalities.
  • Neuroimaging plays a crucial role in diagnosing and understanding the spectrum of Menkes disease.

Observation:

  • A pediatric patient diagnosed with Menkes disease presented with specific neuroimaging findings.
  • Magnetic Resonance Imaging (MRI) was utilized to evaluate the brain structure and vascularity.
  • The patient also exhibited features consistent with a Dandy-Walker variant.

Findings:

  • MRI revealed delayed myelination of the brain's white matter, a key indicator of impaired neurological development.
  • Evidence of brain atrophy was observed, suggesting neuronal loss or reduced brain volume.
  • Tortuosity of the intracranial vessels was a prominent feature, consistent with vascular abnormalities seen in Menkes disease.
  • The coexistence of characteristic Menkes disease MRI findings and a Dandy-Walker variant was noted.

Implications:

  • This case underscores the importance of advanced neuroimaging in diagnosing Menkes disease and its associated structural anomalies.
  • Understanding the MRI spectrum can aid in earlier diagnosis and management of affected children.
  • The co-occurrence of Dandy-Walker variant warrants further investigation into potential sharedPathophysiological mechanisms or diagnostic challenges.

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