Maxillary reconstruction for a huge odontogenic keratocyst

A range of different entities may be responsible for cystic lesions in the maxillary region. However, sometimes an accurate diagnosis cannot be made based on clinical or radiologic presentation. In this case, the surgeon should evaluate the clinical situation so that a comprehensive surgical plan that addresses the patient's complaints can be made. We present a 25-year-old female patient with a huge maxillary cyst causing obvious cheek protrusion. For cosmetic concern, she received surgical excision of the cystic lesion and reconstruction of anterior maxillary defect. No recurrence was seen at 18 months' follow-up, and the patient was quite satisfied with the aesthetic result. We reported the case to provide an effective procedure for benign maxillary cysts that result in cosmetic concerns with simple excision and reconstruction.