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Published on: March 12, 2013
A novel PITX2c loss‑of‑function mutation underlies lone atrial fibrillation
Yi-Meng Zhou1, Peng-Xiang Zheng, Yi-Qing Yang
1The Key Laboratory of Cardiovascular Remodeling and Function Research, Chinese Ministry of Education and Chinese Ministry of Health, Shandong University Qilu Hospital, Jinan, Shandong 250012, PR China.
Insights
Genetic defects in the PITX2c gene are linked to lone atrial fibrillation (AF). A novel loss-of-function mutation was identified, offering insights into AF mechanisms and potential therapies.
Area of Science:
- Cardiovascular Genetics
- Molecular Cardiology
- Cardiac Arrhythmias
Background:
- Atrial fibrillation (AF) is a prevalent cardiac arrhythmia with significant morbidity and mortality.
- Genetic factors play a role in AF pathogenesis, but determinants remain largely unknown.
- Lone AF suggests a primary genetic basis, necessitating investigation into candidate genes.
Purpose of the Study:
- To investigate the role of the PITX2c gene in the etiology of lone atrial fibrillation.
- To identify novel genetic mutations in PITX2c associated with AF.
- To functionally characterize the impact of identified mutations on PITX2c activity.
Main Methods:
- Sequencing of the PITX2c gene in 100 lone AF patients and 200 controls.
- In silico prediction of mutation pathogenicity (MutationTaster, PolyPhen-2).
- Functional assessment using a dual-luciferase reporter assay.
Main Results:
- A novel heterozygous PITX2c mutation (p.T97A) was identified in an AF patient.
- The mutation was absent in controls and predicted to be disease-causing.
- Functional assays revealed significantly decreased transcriptional activity of the mutant PITX2c protein.
Conclusions:
- This study provides the first evidence linking a PITX2c loss-of-function mutation to lone AF.
- The findings enhance understanding of AF molecular mechanisms.
- This discovery suggests potential for early prophylaxis and allele-specific therapies for AF.
Abstract:
Atrial fibrillation (AF) is the most common form of sustained cardiac arrhythmia responsible for substantial morbidity and significantly increased mortality rates. A growing body of evidence documents the important role of genetic defects in the pathogenesis of AF. However, AF is a heterogeneous disease and the genetic determinants for AF in an overwhelming majority of patients remain unknown. In the present study, a cohort of 100 unrelated patients with lone AF and a total of 200 unrelated, ethnically matched healthy individuals used as controls, were recruited. The whole coding exons and splice junctions of the pituitary homeobox 2c (PITX2c) gene, which encodes a paired‑like homeobox transcription factor required for normal cardiovascular morphogenesis, were sequenced in the 100 patients and 200 control subjects. The causative potential of the identified mutation of PITX2c was predicted by MutationTaster and PolyPhen‑2. The functional characteristics of the PITX2c mutation were assayed using a dual‑luciferase reporter assay system. Based on the results, a novel heterozygous PITX2c mutation (p.T97A) was identified in a patient with AF. The missense mutation was absent in the 400 reference chromosomes and was automatically predicted to be disease‑causing. Multiple alignments of PITX2c protein sequences across species revealed that the altered amino acid was completely conserved evolutionarily. Functional analysis demonstrated that the mutant PITX2c protein was associated with significantly decreased transcriptional activity when compared with its wild‑type counterpart. The findings of the present study firstly link the PITX2c loss‑of‑function mutation to lone AF, and provide novel insight into the molecular mechanisms underlying AF, suggesting the potential implications for the early prophylaxis and allele‑specific therapy of this common type of arrhythmia.
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