Late diagnosis of a truncating WISP3 mutation entails a severe phenotype of progressive pseudorheumatoid dysplasia
Salem Alawbathani1,2, Amit Kawalia1, Mert Karakaya3,4
1Cologne Center for Genomics (CCG), 50931 Cologne, Germany.
Insights
Diagnosing rare progressive pseudorheumatoid dysplasia (PPD) early is crucial. Genetic testing identified a WISP3 mutation in siblings, highlighting the need for timely intervention to reduce disease severity.
Area of Science:
- Genetics
- Rare Diseases
- Skeletal Dysplasias
Background:
- Progressive pseudorheumatoid dysplasia (PPD) is a rare, autosomal recessive skeletal dysplasia.
- Delayed diagnosis of rare diseases like PPD can lead to suboptimal medical management and severe phenotypes.
Observation:
- Two siblings presented with a severe phenotype of PPD, with symptom onset at age 3.
- Initial misdiagnosis occurred due to muscle wasting, weakness, and lack of laboratory testing.
Findings:
- Targeted next-generation sequencing identified a homozygous frameshift mutation in the WISP3 gene (c.868_869delAG, p.Ser290Leufs*12).
- This genetic finding confirmed the diagnosis of PPD in the affected siblings.
Implications:
- Early diagnosis of PPD through genetic testing is essential for effective management.
- Timely intervention may mitigate disease severity and prevent complications in patients with WISP3 mutations.
Abstract:
Rare diseases are often misdiagnosed or receive a delayed diagnosis; thus, unfortunately, affected individuals may not receive optimal medical management. Here, we report a case of two siblings with a severe phenotype of progressive pseudorheumatoid dysplasia (PPD). Their onset of symptoms began at the age of 3 yr. Both were neglected in the past, and the patients presented with a very severe phenotype and unmitigated natural history. PPD is a rare autosomal recessive skeletal dysplasia characterized by progressive joint stiffness, swelling, and pain. Because of observed muscle wasting, weakness, and the lack of laboratory testing, the case had been initially misdiagnosed by the local physicians. We aimed to provide diagnostic support by a targeted next-generation sequencing gene panel (Illumina TruSight One) for Mendelian diseases (Mendeliome), and we identified a homozygous frameshift mutation in the gene WISP3 (c.868_869delAG, p.Ser290Leufs*12). Thus, early diagnosis and intervention may have decreased the severity and complication of the disease.
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