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KCNQ2 mutation in an infant with encephalopathy of infancy with migrating focal seizures
Alexander Freibauer1, Kevin Jones2
1McMaster Medical School.
Insights
A rare KCNQ2 gene mutation caused severe infantile seizures and a devastating neurological condition. This case highlights the importance of genetic testing for early diagnosis and potential targeted therapies in KCNQ2 encephalopathy.
Area of Science:
- Neuroscience
- Genetics
- Pediatric Neurology
Background:
- Neonatal seizures require prompt diagnosis and management to prevent long-term neurological sequelae.
- Genetic epilepsies are increasingly recognized as a significant cause of severe early-onset epilepsy.
Observation:
- A male neonate presented with refractory seizures, electrographic status epilepticus, and septic shock.
- Despite aggressive treatment including phenobarbital coma, ketamine infusion, and ketogenic diet, the infant's condition remained critical.
- Posthumous genetic testing identified a de novo KCNQ2 pathogenic variant.
Findings:
- The patient exhibited a rare phenotype of encephalopathy of infancy with migrating focal seizures.
- This is the third reported case linking KCNQ2 mutations to this specific severe epilepsy syndrome.
- The identified KCNQ2 p.Ser247Leu variant is considered likely pathogenic.
Implications:
- This case underscores the critical role of genetic diagnostics in understanding severe neonatal epilepsies.
- Further research into KCNQ2 channelopathies may reveal novel therapeutic targets for KCNQ2 encephalopathy.
- Understanding the cellular mechanisms of KCNQ2 variants is crucial for developing effective treatments.
Abstract:
A male neonate presented with seizures at 18 hours of life, characterized by tonic posturing with eye deviation to the right, apnoea, bradycardia, and oxygen desaturation. Initial structural, metabolic, and infectious work-up was unremarkable. He continued to have seizures refractory to a variety of antiepileptic medications. A phenobarbital coma was trialled, leading to cessation of clinical seizures but continuation of electrographic status epilepticus. On EEG, ictal discharges originated from both the right and left hemispheres, migrating to the opposite hemisphere, consistent with encephalopathy of infancy with migrating focal seizures. At this time, he developed septic shock and was trialled on a ketamine infusion and ketogenic diet. Due to his poor prognosis, a goals of care discussion was carried out with the family, leading to withdrawal of care and his subsequent death at one month and seven days. A posthumous genetic panel revealed a de novo KCNQ2 p.Ser247Leu variant, considered likely to be pathogenic. This is the third reported case of a KCNQ2 mutation associated with an encephalopathy of infancy with migrating focal seizures phenotype. We discuss potential cellular mechanisms underlying this unique KCNQ2 phenotype, as well as future therapeutic considerations.
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Seizures: Classification
Seizures are typically classified into two main categories: focal and generalized seizures.
Focal Seizures
Focal seizures originate from specific regions of the brain. These seizures are further sub-classified into two types:
Mutation, Gene Flow, and Genetic Drift

