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Dilated Cardiomyopathy due to the Novel MT-CYB Missense Mutation m.14757T>C
Sinda Zarrouk1, Josef Finsterer2, Sounira Mehri1
1Department of Genetic and Molecular Epidemiology, Medical University of Tunis, Tunisia.
Insights
A novel mitochondrial DNA mutation, m.14757T>C in MT-CYB, is linked to dilated cardiomyopathy (DCM). This finding highlights the role of mitochondrial genetic defects in heart disease development.
Area of Science:
- Genetics
- Cardiology
- Mitochondrial Biology
Background:
- Mitochondrial DNA (mtDNA) mutations are associated with multisystem disorders, including cardiomyopathy (CM).
- Mutations in protein-encoding mtDNA genes, like cytochrome-b, have been implicated in CM.
- Dilated cardiomyopathy (DCM) is a significant cardiac condition often requiring further etiological investigation.
Observation:
- A clinical, biochemical, and molecular genetic analysis was conducted on a 40-year-old male patient diagnosed with DCM.
- Muscle biopsy revealed a deficiency in complex-III activity.
- Genetic sequencing identified a novel variant, m.14757T>C, in the MT-CYB gene.
Findings:
- The identified MT-CYB variant (m.14757T>C) results in a methionine to threonine substitution (M4T) at position 4.
- Bioinformatic analysis using PolyPhen predicted the variant as pathogenic.
- This mutation was absent in 2,704 healthy controls and previously unreported as a neutral polymorphism, supporting its pathogenicity.
Implications:
- The novel MT-CYB variant m.14757T>C is associated with dilated cardiomyopathy.
- This discovery suggests a potential pathophysiological role for this specific mtDNA variant in the development of DCM.
- Further research into mitochondrial genetic defects can improve diagnosis and understanding of cardiomyopathies.
Abstract:
Mitochondrial DNA (mtDNA) mutations frequently manifest with multisystem disease, including cardiomyopathy (CM). Various studies described mutations in protein-encoding mtDNA genes, such as cytochrome-b, manifesting with CM. A detailed clinical, biochemical, and molecular genetic analysis was performed in a 40-year-old male with dilated CM (DCM) to detect the underlying mtDNA defect. Muscle biopsy showed complex-III deficiency, and sequencing of the cytochrome-b gene revealed the pathogenic variant m.14757T>C in MT-CYB, resulting in the replacement of the hydrophobic methionine by the polar threonine (M4T). By application of the PolyPhen algorithm the variant was predicted as pathogenic. The mutation was not found in 100 healthy controls and never reported as a neutral polymorphism despite extensive sequencing of the cytochrome-b gene in 2,704 normal healthy controls from different ethnic backgrounds. In conclusion, the novel variant m.14757T>C in MT-CYB is associated with DCM suggesting a pathophysiologic role of the variant in the development of DCM.
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