Combined central and peripheral demyelination: a case report resembling encephalomyeloradiculoneuropathy

Xuan Zhou1, Ali Peng1, Chuan Li1

  • 1Department of Neurology, Tangdu Hospital, Air Force Medical University, Xi'an, Shaanxi Province, China.

Frontiers in Neurology
|January 31, 2024
PubMed

Insights

This case report details a rare instance of combined central and peripheral demyelination (CCPD) in a teenager, potentially triggered by hepatitis E virus (HEV) infection. Treatment with immunotherapy led to significant clinical improvement, showing CCPD

Area of Science:

  • Neurology
  • Immunology
  • Infectious Diseases

Background:

  • Combined central and peripheral demyelination (CCPD) is an exceptionally rare autoimmune disorder affecting both the central and peripheral nervous systems.
  • The etiology and optimal treatment strategies for CCPD remain poorly understood due to its rarity and heterogeneous presentation.

Observation:

  • A 14-year-old patient presented with acute myelitis (AM), later developing symptoms indicative of Guillain-Barré syndrome (GBS).
  • Nerve conduction studies (NCV) and cerebrospinal fluid (CSF) analysis confirmed the diagnosis of GBS.
  • The patient exhibited abdominal pain and abnormal liver function, identified as hepatitis E virus (HEV) infection, potentially triggering the neurological symptoms.

Findings:

  • The patient received a combination of corticosteroids, intravenous immunoglobulin, and Rituximab.
  • Therapeutic intervention resulted in notable symptom relief and clinical recovery during follow-up.
  • This case suggests that CCPD, despite its severity, may be responsive to immunotherapy and potentially reversible.

Implications:

  • This report underscores the importance of considering HEV infection as a potential trigger for GBS and CCPD.
  • The successful treatment outcome highlights the potential efficacy of immunomodulatory therapies in managing CCPD.
  • There is a critical need for standardized diagnostic criteria and evidence-based treatment guidelines for this rare condition.