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Persistent primitive hypoglossal artery associated with arteriovenous malformation--case report
K Yamanaka1, K Noguchi, K Hayasaki
1Department of Neurosurgery, Hayashi Hospital, Osaka, Japan.
Neurologia Medico-Chirurgica
|November 1, 1990
Summary
A rare case of persistent primitive hypoglossal artery (PPHA) associated with an arteriovenous malformation (AVM) was successfully treated with complete surgical removal. This case highlights a rare but treatable condition involving vascular anomalies.
Area of Science:
- Neurology
- Neurosurgery
- Vascular Medicine
Background:
- Persistent primitive hypoglossal artery (PPHA) is a rare congenital vascular anomaly.
- Intracranial arteriovenous malformations (AVMs) are complex vascular lesions that can lead to hemorrhage.
- The co-occurrence of PPHA and intracranial AVM is exceptionally uncommon.
Observation:
- A 46-year-old male presented with sudden severe headache and transient unconsciousness, indicative of subarachnoid hemorrhage.
- Computed tomography and angiography revealed a left cerebellar hemisphere AVM associated with an ipsilateral PPHA.
- This represents the fourth reported case of PPHA associated with an intracranial AVM.
Findings:
- The patient underwent complete surgical resection of the arteriovenous malformation.
- The patient recovered without neurological deficit and was discharged within one month.
- This is the first reported case of PPHA associated with AVM treated by total AVM removal.
Implications:
- The successful surgical management of this rare PPHA-AVM complex suggests that complete resection is a viable treatment option.
- This case contributes to the limited literature on PPHA-AVM, emphasizing its rarity (3.0% of reported PPHA cases).
- Further research into the embryological basis and optimal management strategies for PPHA-AVM is warranted.