Rare location of Castleman disease in the temporal region

Castleman disease is a lymphocytic hyperplastic disease that is also known as angiofollicular lymphoid hyperplasia or giant lymph node hyperplasia. It occurs mainly in the mediastinum but rarely in the face. Our experience is a case of a 65-year-old man who had a slow-growing, nontender temporal mass for 1 year. Computed tomographic scans showed a 6.0 x 2.5 x 4.5-cm, homogenous and moderately enhanced soft tissue mass in the left temporal region. The mass was excised with caution to avoid injuries to the superficial temporal artery and facial nerve. Frozen section showed lymphoid hyperplasia lesion without malignancy. To the best of our knowledge, this is the first case of Castleman disease that presented in the temporal region; thus, for the first time, we report this case along with the review of the literature.