Hirschsprung's disease manifested with obstructive colitis in adult: a case report

Hirschsprung's disease rarely occurs in adult. If it occurs, the symptoms and signs are usually milder than those in children and manifest in form of chronic or intermittent constipation. Definite surgical intervention could be performed with good results. We reported a 36-year-old male adult with Hirschsprung's disease who manifested as obstructive colitis. The clinical course presented as abdominal fullness and pain, and colonoscopy revealed ulcerations and pseudopolyps formation in the sigmoid colon and rectum. Ganglion was absent in transanal rectal biopsy. Soave's procedure with protective ileostomy was done. Patient's bowel movements turned normal after closure of ileostomy three months later. The literature was also reviewed.