Atypical case of periapical adenomatoid odontogenic tumour

The Adenomatoid Odontogenic Tumour (AOT) is a progressively growing asymptomatic benign non-invasive lesion. A rare subvariant of the extrafollicular type of AOT may mimic periapical disease radiographically. We report a 45-year-old male with a periapical radiolucent lesion affecting maxillary central incisor tooth. Initially suspicious of periapical pathology, although clinical findings seemed to indicate a nonendodontic cause. The lesion was surgically explored and histopathological examination revealed the presence of AOT. This particular subvariant is very rare indeed, as available literature only 8 cases have been reported.